HANFORD THYROID DISEASE STUDY FINAL REPORT

14,1
MB

614
stron

5426
ID Centers for Disease Control and Prevention

2002
rok

TABLE OF CONTENTS

EXECUTIVE SUMMARY

I. INTRODUCTION .....1

II. BACKGROUND ....4

A. Historical Perspective ....4

B. Ionizing Radiation and Thyroid Disease ....9

B.1. Thyroid Neoplasia: Exposure to External Photon Radiation ....9

B.2. Thyroid Neoplasia: Exposure to Radioactive Iodine ...10

B.2.a. Medical Exposures to Radioiodine ..10

B.2.b. Environmental Exposures to Radioiodine ...11

B.2.b.1. Utah .11

B.2.b.2. Marshall Islands ....11

B.2.b.3 Chernobyl ..12

B.2.c. Relative Biological Effectiveness of I-131 in the Induction of

Thyroid Cancer .13

B.3. Hypothyroidism ...14

B.4. Autoimmune Thyroiditis ..14

C. Ionizing Radiation and Parathyroid Disease ...16

C.1. Hyperparathyroidism: Exposure to External Photon Radiation .....16

C.2. Hyperparathyroidism: Exposure to Radioactive Iodine ..17

D. Ultrasound-Detected Abnormalities of the Thyroid (Thyroid UDAs) .....18

D.1. Prevalence of Thyroid UDAs .18

D.2. Specificity of Thyroid Ultrasonography in Predicting Thyroid Cancer ...19

D.3. Ionizing Radiation and Thyroid UDAs .20

III. STUDY OBJECTIVES ...21

IV. STUDY DESIGN .....22

A. Eligibility Criteria ....22

A.1. Mother's Residence at the Time of the Particpant's Birth ....22

A.2. Year of Birth .....30

A.3. Other Possible Criteria ....33

B. Definition of Evaluable Participant ..34

C. Outcome Criteria ..35

C.1. Thyroid Cancer ....35

C.2. Benign Thyroid Nodule .....35

C.3. Any Thyroid Nodule .36

C.4. Hypothyroidism ...36

C.5. Autoimmune (Hashimoto’s) Thyroiditis ..36

C.6. Graves Disease ....37

C.7. Autoimmune Thyroid Disease ..37

C.8. Hyperthyroidism ..37

C.9. Multinodular Thyroid Gland ....38

C.10. Simple Goiter ....38

C.11. Other Thyroid Disease .....38

C.12. Ultrasound-Detected Abnormalities of the Thyroid (Thyroid UDAs) ..39

C.13. Hyperparathyroidism ...39

V. FIELD PROCEDURES AND METHODS, RESULTS OF DATA COLLECTION PROCESS ....40

A. Cohort Definition, Subject Identification and Selection ..40

A.1. Background ..40

A.1.a. Objectives .....40

A.1.b. Definition of the Cohort ...40

A.2. Plan ..41

A.2.a. Protocol Plan ...41

A.2.a.1. Rationale ...41

A.2.a.2. Completeness Required for Success ....43

A.2.b. Plans for Assessing the Need for Change in the Full Study ....43

A.3. Revisions .44

A.3.a. Rationale for Revisions made in the Transition Sample ..44

A.3.b. Rationale for Revisions made in the Full Study ..44

A.4. Outcome and Final Results .45

A.5. Summary of Full Study Power Calculations, as Presented in HTDS Pilot Study Report 47

B. Tracing Potential Participants ..52

B.1. Background .52

B.1.a. Objectives of Tracing ..52

B.1.b. History of Tracing Efforts Around Hanford 52

B.1.c. Overview of Tracing Efforts 53

B.1.d. Staffing and Logistics ..55

B.2. Revisions to the Original Protocol Plan ..55

B.2.a. Deletion of Ineffective Sources of Information and Addition of New Sources .55

B.2.b. Addition of Computer On-line Database Information .56

B.3. Final Tracing Process ..56

B.3.a. Linkages with Publicly Available Data Sources ..56

B.3.b. Manual Tracing Resources ..58

B.3.c. Unlocated Potential Participants .63

B.4. Outcome and Final Results ..68

B.4.a. Results from the Pilot Study Sample .68

B.4.a.1. Results by Strata .68

B.4.b. Results from Transition Sample 68

B.4.b.1. Results by Strata .68

B.4.c. Results for the Full Study Sample 75

B.4.c.1. Results by Strata .76

B.4.d. Overall Results for the Full Study 78

B.4.d.1. Success in Locating Study Potential Participants ..78

B.4.d.2. Current Residence of Living Potential Participants 81

B.4.d.3. Death Certificates Obtained for Deceased Potential Participants .82

C. Recruiting .84

C.1. Background ..84

C.1.a. Objectives of Recruiting ..84

C.2. Recruiting Procedures 84

C.2.a. Initial Written Contact and Attempt to Contact by Phone ..84

C.2.b. Telephone Contact with the Potential Participant ..85

C.2.c. Confirmation of Agreement to Participate and Six Month Letter 86

C.2.d. Refusals and Second Attempts .86

C.2.e. Second Request for Participation 86

C.3. Outcome and Results 87

C.3.a. Results for the Pilot Study Sample ..87

C.3.b. Results from the Transition Sample .91

C.3.c. Results for the Full Study Sample 95

C.3.d. Results for the Entire Study .98

C.3.d.1. Agreement on First Attempt vs. Second Attempt (conversions) 102

C.3.d.2. Refusal 103

C.3.d.3. Success in Converting Refusals/Withdrawals by Reason for Refusal .104

C.3.d.4. Success in Converting Refusals/Withdrawals by “Strength” of Refusal 105

C.3.e. Conclusions ...106

D. Computer Assisted Telephone Interview ..107

D.1. Background ...107

D.1.a. Objectives of the Interview 107

D.1.b. Historical Perspective and Special Challenges .107

D.2. Content and Design of the CATI ...108

D.2.a. Development of a Cognitive Approach to Enhance Long-term Recall ....108

D.2.b. Development and Testing of the CATI ..109

D.2.c. Final Process and Procedures ..110

D.2.c.1. Conducting the Interview ..110

D.2.c.2. Quality Control ....111

D.3. Outcome and Results .112

D.3.a. Pilot Study Results ....112

D.3.b. Transition Sample Results .112

D.3.c. Results for the Full Study Sample .112

D.3.d. Overall Results for the Entire Study 112

D.3.e. Conclusions ..112

D.3.e.1. Quality of the Data 113

D.4. Attempts to Administer the CATI to Respondents for Deceased Potential Participants ..115

D.4.a. Development of a Revised CATI for Deceased Potential Participants ..115

D.4.b. Conducting a CATI for Deceased Potential Participants .116

D.5. Success of the CATI Component ...116

E. Scheduling 118

E.1. Background 118

E.2. Objectives of Scheduling 118

E.3. Final Process and Procedures 119

E.4. Outcome .120

E.4.a. Results for the Pilot Study Sample .120

E.4.b. Results for the Transition Sample ..120

E.4.c. Results for the Full Study Sample ..121

E.4.d. Overall Results for the Entire Study121

E.4.e. Conclusions 124

F. Clinical Evaluation 125

F.1. Background ...125

F.1.a. Objectives for Clinical Evaluations ..125

F.1.b. Rationale ...125

F.2. Clinic Procedures ..125

F.2.a. Clinic Locations and Schedules .125

F.2.b. Clinical Evaluation Process ..125

F.2.c. Clinic Staffing 126

F.2.d. Efforts to Reduce Physician and Ultrasonographer Bias .126

F.3. Serum Sample 127

F.3.a. Laboratory Studies ..127

F.3.b. Changes in Laboratory Assays ..127